Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000515791 | SCV004298979 | pathogenic | X-linked lymphoproliferative disease due to XIAP deficiency | 2023-02-22 | criteria provided, single submitter | clinical testing | ClinVar contains an entry for this variant (Variation ID: 446508). This sequence change creates a premature translational stop signal (p.Asn341Tyrfs*8) in the XIAP gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in XIAP are known to be pathogenic (PMID: 17080092, 21119115, 25666262). This variant is not present in population databases (gnomAD no frequency). This premature translational stop signal has been observed in individual(s) with XIAP deficiency (PMID: 22228567). For these reasons, this variant has been classified as Pathogenic. |
OMIM | RCV000515791 | SCV000611883 | pathogenic | X-linked lymphoproliferative disease due to XIAP deficiency | 2017-12-05 | no assertion criteria provided | literature only |