Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001857042 | SCV002136166 | pathogenic | not provided | 2024-10-08 | criteria provided, single submitter | clinical testing | This sequence change replaces threonine, which is neutral and polar, with methionine, which is neutral and non-polar, at codon 811 of the ABCC6 protein (p.Thr811Met). This variant is present in population databases (rs72653796, gnomAD 0.01%). This missense change has been observed in individual(s) with pseudoxanthoma elasticum (PMID: 16410789, 32873932). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. ClinVar contains an entry for this variant (Variation ID: 433275). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is expected to disrupt ABCC6 protein function with a positive predictive value of 95%. Experimental studies have shown that this missense change affects ABCC6 function (PMID: 30154241). For these reasons, this variant has been classified as Pathogenic. |
Genomic Medicine Center of Excellence, |
RCV000499238 | SCV005442047 | likely benign | Autosomal recessive inherited pseudoxanthoma elasticum | 2024-12-19 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV005010420 | SCV005638894 | pathogenic | Autosomal recessive inherited pseudoxanthoma elasticum; Pseudoxanthoma elasticum, forme fruste; Arterial calcification, generalized, of infancy, 2 | 2024-04-12 | criteria provided, single submitter | clinical testing | |
PXE International | RCV000499238 | SCV000589008 | pathogenic | Autosomal recessive inherited pseudoxanthoma elasticum | 2021-03-01 | no assertion criteria provided | research |