Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
PXE International | RCV000499181 | SCV000589033 | uncertain significance | Autosomal recessive inherited pseudoxanthoma elasticum | 2021-02-02 | criteria provided, single submitter | research | |
Labcorp Genetics |
RCV001857044 | SCV002182613 | uncertain significance | not provided | 2024-12-16 | criteria provided, single submitter | clinical testing | This sequence change replaces leucine, which is neutral and non-polar, with histidine, which is basic and polar, at codon 953 of the ABCC6 protein (p.Leu953His). This variant is present in population databases (rs72657700, gnomAD 0.004%). This missense change has been observed in individual(s) with clinical features of pseudoxanthoma elasticum (PMID: 11536079, 34906475). ClinVar contains an entry for this variant (Variation ID: 433297). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is expected to disrupt ABCC6 protein function with a positive predictive value of 95%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Revvity Omics, |
RCV001857044 | SCV003824354 | uncertain significance | not provided | 2021-06-24 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV005010422 | SCV005638874 | likely pathogenic | Autosomal recessive inherited pseudoxanthoma elasticum; Pseudoxanthoma elasticum, forme fruste; Arterial calcification, generalized, of infancy, 2 | 2024-03-01 | criteria provided, single submitter | clinical testing |