Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institut de Recherche Interdisciplinaire en Biologie Humaine et Moleculaire, |
RCV000000073 | SCV000998514 | likely pathogenic | Microcephaly 9, primary, autosomal recessive | criteria provided, single submitter | clinical testing | ||
Ce |
RCV003390627 | SCV004129836 | pathogenic | not provided | 2023-10-01 | criteria provided, single submitter | clinical testing | CEP152: PVS1, PM2 |
Labcorp Genetics |
RCV003390627 | SCV004297262 | pathogenic | not provided | 2023-09-09 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. ClinVar contains an entry for this variant (Variation ID: 56). This premature translational stop signal has been observed in individual(s) with CEP152-related conditions (PMID: 20598275). This variant is present in population databases (rs267606718, gnomAD 0.004%). This sequence change creates a premature translational stop signal (p.Arg987*) in the CEP152 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in CEP152 are known to be pathogenic (PMID: 21131973). |
OMIM | RCV000000073 | SCV000020216 | pathogenic | Microcephaly 9, primary, autosomal recessive | 2010-07-09 | no assertion criteria provided | literature only |