Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV005090991 | SCV005834174 | uncertain significance | Primary pulmonary hypertension | 2024-11-12 | criteria provided, single submitter | clinical testing | This sequence change falls in intron 9 of the BMPR2 gene. It does not directly change the encoded amino acid sequence of the BMPR2 protein. It affects a nucleotide within the consensus splice site. This variant is not present in population databases (gnomAD no frequency). This variant has been observed in individuals with pulmonary hypertension (PMID: 16429395). ClinVar contains an entry for this variant (Variation ID: 425912). Variants that disrupt the consensus splice site are a relatively common cause of aberrant splicing (PMID: 17576681, 9536098). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. This variant disrupts the c.1276+3A nucleotide in BMPR2. Other variant(s) that disrupt this nucleotide have been observed in individuals with BMPR2-related conditions (PMID: 20534176), which suggests that this may be a clinically significant nucleotide. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Rare Disease Genomics Group, |
RCV000488854 | SCV000576206 | pathogenic | Pulmonary hypertension, primary, 1 | no assertion criteria provided | literature only |