Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
3billion, |
RCV001808258 | SCV002058891 | pathogenic | Deficiency of iodide peroxidase | 2022-01-03 | criteria provided, single submitter | clinical testing | Stop-gained (nonsense): predicted to result in a loss or disruption of normal protein function through nonsense-mediated decay (NMD) or protein truncation. Multiple pathogenic variants are reported downstream of the variant (PVS1_VS).The variant has been reported to be associated with TPO related disorder (PMID:23236987). It is observed at an extremely low frequency in the gnomAD v2.1.1 dataset (total allele frequency: 0.000040, PM2_M). Each parent is heterozygous for the variant (PM3_P, 3billion dataset). Therefore, this variant is classified as pathogenic according to the recommendation of ACMG/AMP guideline. |
Labcorp Genetics |
RCV003560858 | SCV004292045 | pathogenic | not provided | 2023-12-13 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Glu596*) in the TPO gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in TPO are known to be pathogenic (PMID: 11061528, 23236987, 25564141). This variant is present in population databases (rs749174434, gnomAD 0.03%). This premature translational stop signal has been observed in individual(s) with thyroid dyshormonogenesis (PMID: 23236987). ClinVar contains an entry for this variant (Variation ID: 1333570). For these reasons, this variant has been classified as Pathogenic. |
Fulgent Genetics, |
RCV001808258 | SCV005652951 | pathogenic | Deficiency of iodide peroxidase | 2024-01-17 | criteria provided, single submitter | clinical testing |