Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001053949 | SCV001218236 | uncertain significance | Primary ciliary dyskinesia | 2024-10-29 | criteria provided, single submitter | clinical testing | This sequence change replaces asparagine, which is neutral and polar, with threonine, which is neutral and polar, at codon 3782 of the DNAH8 protein (p.Asn3782Thr). This variant is present in population databases (rs150057448, gnomAD 0.02%). This variant has not been reported in the literature in individuals affected with DNAH8-related conditions. ClinVar contains an entry for this variant (Variation ID: 849895). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is expected to disrupt DNAH8 protein function with a positive predictive value of 80%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Fulgent Genetics, |
RCV002481983 | SCV002804000 | uncertain significance | Spermatogenic failure 46 | 2021-11-24 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV004619496 | SCV005119187 | uncertain significance | not specified | 2024-04-23 | criteria provided, single submitter | clinical testing | The c.11345A>C (p.N3782T) alteration is located in exon 76 (coding exon 75) of the DNAH8 gene. This alteration results from a A to C substitution at nucleotide position 11345, causing the asparagine (N) at amino acid position 3782 to be replaced by a threonine (T). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |