Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV003035827 | SCV003343629 | uncertain significance | Mosaic variegated aneuploidy syndrome 1 | 2022-04-10 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Tolerated"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C0"). This variant has not been reported in the literature in individuals affected with BUB1B-related conditions. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces histidine, which is basic and polar, with tyrosine, which is neutral and polar, at codon 968 of the BUB1B protein (p.His968Tyr). |
Ambry Genetics | RCV004963352 | SCV005546119 | uncertain significance | Inborn genetic diseases | 2024-08-07 | criteria provided, single submitter | clinical testing | The p.H968Y variant (also known as c.2902C>T), located in coding exon 22 of the BUB1B gene, results from a C to T substitution at nucleotide position 2902. The histidine at codon 968 is replaced by tyrosine, an amino acid with similar properties. This amino acid position is conserved. In addition, this alteration is predicted to be tolerated by in silico analysis. Based on the available evidence, the clinical significance of this variant remains unclear. |