Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ce |
RCV001091235 | SCV001247145 | pathogenic | not provided | 2018-11-01 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001225906 | SCV001398200 | likely pathogenic | Cryopyrin associated periodic syndrome | 2020-04-12 | criteria provided, single submitter | clinical testing | This variant is not present in population databases (ExAC no frequency). In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. This variant disrupts the p.Ala354 amino acid residue in NLRP3. Other variant(s) that disrupt this residue have been observed in individuals with NLRP3-related conditions (PMID: 26931528), which suggests that this may be a clinically significant amino acid residue. This variant has been reported to affect NLRP3 protein function (PMID: 19501000, 29322034). This variant has been observed to segregate with Muckle-Wells syndrome in a family and has been reported in unrelated individuals affected with cryopyrin-associated periodic syndrome (PMID: 11687797, 30431487, 21109514, 29047407). This variant is also known as p.Ala352Val in the literature. ClinVar contains an entry for this variant (Variation ID: 4373). This sequence change replaces alanine with valine at codon 354 of the NLRP3 protein (p.Ala354Val). The alanine residue is highly conserved and there is a small physicochemical difference between alanine and valine. |
OMIM | RCV000004621 | SCV000024795 | pathogenic | Familial amyloid nephropathy with urticaria AND deafness | 2001-11-01 | no assertion criteria provided | literature only | |
Unité médicale des maladies autoinflammatoires, |
RCV000084171 | SCV000116302 | not provided | Familial cold autoinflammatory syndrome 1 | no assertion provided | not provided |