Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Laboratory of Medical Genetics, |
RCV001730028 | SCV001976779 | likely pathogenic | HNSHA due to aldolase A deficiency | 2021-08-10 | criteria provided, single submitter | clinical testing | PM2, PM3, PP3, PP5 |
Labcorp Genetics |
RCV001730028 | SCV004297715 | pathogenic | HNSHA due to aldolase A deficiency | 2022-10-27 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive. ClinVar contains an entry for this variant (Variation ID: 1299556). This missense change has been observed in individual(s) with aldolase A deficiency (PMID: 25392908, 33665120). It has also been observed to segregate with disease in related individuals. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces alanine, which is neutral and non-polar, with valine, which is neutral and non-polar, at codon 280 of the ALDOA protein (p.Ala280Val). |