Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000796680 | SCV000936203 | uncertain significance | 3-methylglutaconic aciduria, type VIIB | 2023-05-12 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with glutamine, which is neutral and polar, at codon 561 of the CLPB protein (p.Arg561Gln). This variant is not present in population databases (gnomAD no frequency). This missense change has been observed in individual(s) with autosomal dominant congenital neutropenia (PMID: 34115842). ClinVar contains an entry for this variant (Variation ID: 643064). An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. This variant disrupts the p.Arg561 amino acid residue in CLPB. Other variant(s) that disrupt this residue have been determined to be pathogenic (PMID: 32313153, 34140661; Invitae). This suggests that this residue is clinically significant, and that variants that disrupt this residue are likely to be disease-causing. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Gene |
RCV001766643 | SCV001998797 | pathogenic | not provided | 2022-07-05 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis, which includes protein predictors and evolutionary conservation, supports a deleterious effect; This variant is associated with the following publications: (PMID: 34140661, 35499078, 34115842) |
Institute of Medical Genetics and Applied Genomics, |
RCV002221585 | SCV005328358 | likely pathogenic | Neutropenia, severe congenital, 9, autosomal dominant | 2024-09-25 | criteria provided, single submitter | clinical testing | |
OMIM | RCV002221585 | SCV002499261 | pathogenic | Neutropenia, severe congenital, 9, autosomal dominant | 2022-04-11 | no assertion criteria provided | literature only |