Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Loeys Lab, |
RCV001375661 | SCV001572589 | pathogenic | Primary dilated cardiomyopathy | 2021-02-26 | criteria provided, single submitter | clinical testing | This sequence change results in a truncating variant of the TTN gene (p.(Ser4531*))The variant is absent in population databases such as gnomAD (PM2) . The variant has not been described before. Functional studies have not been performed. However truncating and frameshift mutations in TTN are a well-known mechanism for dilated cardiomyopathy (PMID: 22335739) (PVS1). This variant was identified in a 7 unrelated patients with DCM, and co-segregated within 4 families, for the other 3 patients no data on segregation was available (PP1). In conclusion this variant was classified as pathogenic according to ACMG-guidelines (PVS1, PM2, PP1). |
Center for Human Genetics, |
RCV001375661 | SCV002817415 | pathogenic | Primary dilated cardiomyopathy | 2022-12-31 | criteria provided, single submitter | clinical testing |