Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Baylor Genetics | RCV000850497 | SCV000992697 | likely pathogenic | Achromatopsia 2 | 2018-10-12 | criteria provided, single submitter | clinical testing | |
Blueprint Genetics | RCV001073600 | SCV001239151 | pathogenic | Retinal dystrophy | 2019-07-12 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001384601 | SCV001584158 | pathogenic | not provided | 2024-02-18 | criteria provided, single submitter | clinical testing | This sequence change replaces aspartic acid, which is acidic and polar, with asparagine, which is neutral and polar, at codon 260 of the CNGA3 protein (p.Asp260Asn). This variant is present in population databases (rs374258471, gnomAD 0.006%). This missense change has been observed in individual(s) with CNGA3-related conditions (PMID: 11536077, 24903488, 26992781, 28159970, 30682209). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. It has also been observed to segregate with disease in related individuals. ClinVar contains an entry for this variant (Variation ID: 689726). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt CNGA3 protein function with a positive predictive value of 95%. Experimental studies have shown that this missense change affects CNGA3 function (PMID: 17693388). For these reasons, this variant has been classified as Pathogenic. |
Institute of Medical Genetics and Applied Genomics, |
RCV001384601 | SCV001905544 | pathogenic | not provided | 2021-09-15 | criteria provided, single submitter | clinical testing | |
Institute of Human Genetics, |
RCV001073600 | SCV005068392 | pathogenic | Retinal dystrophy | 2023-01-01 | criteria provided, single submitter | clinical testing | |
Gene |
RCV001384601 | SCV005421324 | pathogenic | not provided | 2024-06-03 | criteria provided, single submitter | clinical testing | Published functional studies demonstrate a damaging effect: damaged cone photoreceptor cGMP-gated cation channel (PMID: 17693388); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 24676353, 26992781, 28159970, 31216405, 11536077, 30682209, 25637600, 19592100, 31964843, 34360608, 35332618, 32531858, 24903488, 35119454, 37372476, 37734845, 17693388) |