Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Prevention |
RCV004364463 | SCV004114224 | uncertain significance | GATA4-related disorder | 2022-10-10 | criteria provided, single submitter | clinical testing | The GATA4 c.1207C>A variant is predicted to result in the amino acid substitution p.Leu403Met. This variant has been reported in individuals with sporadic hypoplastic right ventricle and atrial septal defect-ventricular septal defect (ASD-VSD) (Rajagopal et al. 2007. PubMed ID: 17643447; Dinesh et al. 2011. PubMed ID: 21631294). Structural analysis of the protein determined that this variant impacts structure (Dinesh et al. 2011. PubMed ID: 21631294). This variant is reported in 0.017% of alleles in individuals of Latino descent in gnomAD (http://gnomad.broadinstitute.org/variant/8-11615862-C-A). At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |
Labcorp Genetics |
RCV003528470 | SCV004291402 | uncertain significance | Atrioventricular septal defect 4 | 2024-03-20 | criteria provided, single submitter | clinical testing | This sequence change replaces leucine, which is neutral and non-polar, with methionine, which is neutral and non-polar, at codon 403 of the GATA4 protein (p.Leu403Met). This variant is present in population databases (rs777778466, gnomAD 0.02%). This missense change has been observed in individual(s) with GATA4-related conditions (PMID: 17643447, 21631294). ClinVar contains an entry for this variant (Variation ID: 2637134). An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. Experimental studies are conflicting or provide insufficient evidence to determine the effect of this variant on GATA4 function (PMID: 35418170). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |