Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001871241 | SCV002144284 | uncertain significance | Joubert syndrome 23; Short-rib thoracic dysplasia 14 with polydactyly | 2022-06-13 | criteria provided, single submitter | clinical testing | This variant has not been reported in the literature in individuals affected with KIAA0586-related conditions. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Benign"; Align-GVGD: "Class C0"). This variant is not present in population databases (gnomAD no frequency). This sequence change replaces aspartic acid, which is acidic and polar, with valine, which is neutral and non-polar, at codon 1317 of the KIAA0586 protein (p.Asp1317Val). |
Ambry Genetics | RCV004041067 | SCV004892334 | uncertain significance | Inborn genetic diseases | 2024-02-12 | criteria provided, single submitter | clinical testing | The c.3563A>T (p.D1188V) alteration is located in exon 24 (coding exon 24) of the KIAA0586 gene. This alteration results from a A to T substitution at nucleotide position 3563, causing the aspartic acid (D) at amino acid position 1188 to be replaced by a valine (V). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |