Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000470915 | SCV000552219 | uncertain significance | Idiopathic generalized epilepsy | 2016-06-01 | criteria provided, single submitter | clinical testing | Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive, but these predictions have not been confirmed by published functional studies. In summary, this variant is a novel missense change with uncertain impact on protein function. It has been classified as a Variant of Uncertain Significance. This variant is not present in population databases (ExAC no frequency) and has not been reported in the literature in individuals with a RBFOX3-related disease. This sequence change replaces proline with threonine at codon 186 of the RBFOX3 protein (p.Pro186Thr). The proline residue is highly conserved and there is a small physicochemical difference between proline and threonine. Comment |