Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Eurofins Ntd Llc |
RCV000339772 | SCV000345155 | uncertain significance | not provided | 2016-08-24 | criteria provided, single submitter | clinical testing | |
Counsyl | RCV000671730 | SCV000796740 | uncertain significance | Smith-Lemli-Opitz syndrome | 2017-12-28 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV001805002 | SCV002051342 | uncertain significance | not specified | 2021-12-23 | criteria provided, single submitter | clinical testing | Variant summary: DHCR7 c.742T>C (p.Trp248Arg) results in a non-conservative amino acid change in the encoded protein sequence. Five of five in-silico tools predict a damaging effect of the variant on protein function. The variant allele was found at a frequency of 4e-06 in 251306 control chromosomes (gnomAD). The available data on variant occurrences in the general population are insufficient to allow any conclusion about variant significance. c.742T>C has been reported in the literature in individuals affected with Smith-Lemli-Opitz Syndrome (Waye_2002, Wassif_2005). These data do not allow any conclusion about variant significance. To our knowledge, no experimental evidence demonstrating an impact on protein function has been reported. Two ClinVar submitters (evaluation after 2014) cite the variant as uncertain significance. Based on the evidence outlined above, the variant was classified as uncertain significance. |