Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Dunham Lab, |
RCV002305734 | SCV002599282 | likely pathogenic | Anemia, nonspherocytic hemolytic, due to G6PD deficiency | 2022-08-12 | criteria provided, single submitter | curation | Variant found in hemizygotes with G6PD deficiency (PP4). Decreased activity in red blood cells (PS3). Below expected carrier frequency in gnomAD (PM2). Predicted to be possibly damaging by PolyPhen and disease causing by Mutation Taster (PP3). Post_P 0.975 (odds of pathogenicity 350.3, Prior_P 0.1). |
Revvity Omics, |
RCV002305734 | SCV003828415 | uncertain significance | Anemia, nonspherocytic hemolytic, due to G6PD deficiency | 2020-03-15 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV005058252 | SCV005726354 | uncertain significance | not specified | 2024-11-13 | criteria provided, single submitter | clinical testing | Variant summary: G6PD c.1420G>A (p.Val474Ile) results in a conservative amino acid change located in the Glucose-6-phosphate dehydrogenase, C-terminal domain (IPR022675) of the encoded protein sequence. Three of five in-silico tools predict a benign effect of the variant on protein function. The variant allele was found at a frequency of 5.5e-06 in 182321 control chromosomes. The available data on variant occurrences in the general population are insufficient to allow any conclusion about variant significance. c.1420G>A has been reported in the literature in individuals affected with Glucose 6 Phosphate Dehydrogenase Deficiency (Chiu_2019, Geck_2023). These reports do not provide unequivocal conclusions about association of the variant with Glucose 6 Phosphate Dehydrogenase Deficiency. To our knowledge, no experimental evidence demonstrating an impact on protein function has been reported. The following publications have been ascertained in the context of this evaluation (PMID: 31294066, 36681081, 32702756, 35845714). ClinVar contains an entry for this variant (Variation ID: 1722624). Based on the evidence outlined above, the variant was classified as uncertain significance. |