Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
NIHR Bioresource Rare Diseases, |
RCV001027580 | SCV001190155 | uncertain significance | Inherited Immunodeficiency Diseases | 2019-01-01 | criteria provided, single submitter | research | |
Labcorp Genetics |
RCV001862407 | SCV002137893 | pathogenic | Combined immunodeficiency due to LRBA deficiency | 2023-12-04 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Arg633*) in the LRBA gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in LRBA are known to be pathogenic (PMID: 26206937, 26768763). This variant is present in population databases (rs770266168, gnomAD 0.004%). This premature translational stop signal has been observed in individual(s) with clinical features of LRBA deficiency (PMID: 32499645). ClinVar contains an entry for this variant (Variation ID: 827711). For these reasons, this variant has been classified as Pathogenic. |