Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Victorian Clinical Genetics Services, |
RCV003225628 | SCV003921819 | uncertain significance | Ehlers-Danlos syndrome due to tenascin-X deficiency | criteria provided, single submitter | clinical testing | - This intragenic copy number variant results in an in-frame deletion of at least exons 24 to 26 (of 44) with no known impact on reading frame. The exact breakpoints have not been determined. Additional information: - Loss of function is a known mechanism of disease in this gene and is associated with classic-like type 1 Ehlers-Danlos syndrome (MIM#606408). - This gene is associated with autosomal recessive disease. - This variant is heterozygous. - Variant is absent from gnomAD (gnomAD SVs v2.1). - This variant is predicted to delete multiple fibronectin type III domains (NCBI). - No comparable in-frame copy number deletions have previous evidence for pathogenicity. - This variant has no previous evidence of pathogenicity. - No published segregation evidence has been identified for this variant. - No published functional evidence has been identified for this variant. - This variant has been shown to be paternally inherited by trio analysis. |