Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001057512 | SCV001222010 | pathogenic | Primary ciliary dyskinesia | 2021-09-29 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Gln1162*) in the DNAH5 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in DNAH5 are known to be pathogenic (PMID: 11788826, 16627867). This variant is present in population databases (rs760081822, ExAC 0.002%). This premature translational stop signal has been observed in individuals with primary ciliary dyskinesia (PMID: 27637300). For these reasons, this variant has been classified as Pathogenic. |
Fulgent Genetics, |
RCV001542575 | SCV005668925 | pathogenic | Primary ciliary dyskinesia 3 | 2024-03-08 | criteria provided, single submitter | clinical testing | |
Genomics England Pilot Project, |
RCV001542575 | SCV001760153 | pathogenic | Primary ciliary dyskinesia 3 | no assertion criteria provided | clinical testing |