Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Human Genetics, |
RCV001374635 | SCV001571225 | likely pathogenic | Intellectual disability, autosomal dominant 30 | 2021-04-13 | criteria provided, single submitter | clinical testing | de novo in an individual with Seizure/epilepsy/Rx: Atypical Benign Partial Epilepsy onset 2y 9mo. Atypical absences with eyelid myoclonia, atonic seizures, focal limb and face myoclonias, non-convulsive status epilepticus, generalised tonic-clonic seizure. EEG: 3y 2mo: Bursts of 2.5 Hz bilateral, frontal predominant spike-waves, along with eyelid myoclonias and slow head drops (atypical absences). Normal background. 3y 11mo: Irritative activity, bilateral, left predominant, left hemispheric intermittent slowing, eyelid myoclonias, subcontinuous spike and wave during sleep.Neuropsych/development: 5yo F. infantile hypotonia, delayed motor development, expressive language difficulties. Normocephalic.. No autism or behavioural problems. Normal MRI. See details in main text.Dysmorphism: Mild hypertelorism, short philtrum, hypoplastic teeth, left divergent strabismus |
Gene |
RCV001664856 | SCV001874729 | likely pathogenic | not provided | 2024-05-31 | criteria provided, single submitter | clinical testing | In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 34216016) |
Clinical Genetics Laboratory, |
RCV001374635 | SCV005873564 | likely pathogenic | Intellectual disability, autosomal dominant 30 | 2023-09-26 | no assertion criteria provided | clinical testing |