Total submissions: 10
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000481866 | SCV000568233 | pathogenic | not provided | 2022-12-08 | criteria provided, single submitter | clinical testing | Nonsense variant predicted to result in protein truncation or nonsense mediated decay in a gene for which loss-of-function is a known mechanism of disease; Not observed in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 30349098, 26350204, 27474218, 34122524, Pagliaroli2021[Functional Study], 31785789, 22426309) |
Ambry Genetics | RCV000624305 | SCV000741656 | pathogenic | Inborn genetic diseases | 2016-07-01 | criteria provided, single submitter | clinical testing | |
Undiagnosed Diseases Network, |
RCV000024215 | SCV000746582 | pathogenic | Coffin-Siris syndrome 1 | 2017-02-17 | criteria provided, single submitter | clinical testing | |
Baylor Genetics | RCV000024215 | SCV000807315 | pathogenic | Coffin-Siris syndrome 1 | 2017-09-01 | criteria provided, single submitter | clinical testing | This mutation has been previously reported as disease-causing and was found once in our laboratory as a de novo finding in a 4-year-old female with global delays, autism, dysmorphic features, fifth finger brachydactyly/nail hypoplasia. |
Génétique des Maladies du Développement, |
RCV000024215 | SCV000890069 | pathogenic | Coffin-Siris syndrome 1 | 2017-10-20 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV000024215 | SCV000893703 | pathogenic | Coffin-Siris syndrome 1 | 2018-10-31 | criteria provided, single submitter | clinical testing | |
Baylor Genetics | RCV001533116 | SCV001748936 | pathogenic | ARID1B-related BAFopathy | 2021-06-10 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV000024215 | SCV002054276 | pathogenic | Coffin-Siris syndrome 1 | 2021-07-15 | criteria provided, single submitter | clinical testing | |
OMIM | RCV000024215 | SCV000045506 | pathogenic | Coffin-Siris syndrome 1 | 2012-03-18 | no assertion criteria provided | literature only | |
Prevention |
RCV004737163 | SCV005353418 | pathogenic | ARID1B-related disorder | 2024-07-03 | no assertion criteria provided | clinical testing | The ARID1B c.3223C>T variant is predicted to result in premature protein termination (p.Arg1075*). This variant has been reported in individual(s) with Coffin-Siris syndrome (see for example, Santen et al 2012. PubMed ID: 22426309). This variant has not been reported in a large population database, indicating this variant is rare. Nonsense variants in ARID1B are expected to be pathogenic. This variant is interpreted as pathogenic. |