Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Molecular Genetics Laboratory, |
RCV004808513 | SCV005431438 | likely pathogenic | Coffin-Siris syndrome 1 | 2024-12-13 | criteria provided, single submitter | clinical testing | This variant was detected in a male with mild intellectual disability, specific articulation disorder, hypotonia, nystagmus, facial dysmorphism, eczematoid dermatitis. The variant was confirmed to be of a de novo origin. Rare missense variants affecting the ARID1B gene are documented as a molecular cause of "Coffin-Siris syndrome 1" (CSS1, OMIM:135900) and ARID1B-related BAFopathy (PMID:30349098;27474218;26376624;25674384). A different missense variant c.3704G>A, p.(Gly1235Asp) on the same position is reported as likely pathogenic.To conclude, the variant is classified as likely pathogenic (ACMG PM2, PS2, PM5, PP3). |