Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Muenke lab, |
RCV000453630 | SCV000510563 | uncertain significance | Holoprosencephaly sequence | criteria provided, single submitter | research | Inherited from an unaffected mother | |
Labcorp Genetics |
RCV002522740 | SCV003459347 | uncertain significance | not provided | 2022-04-16 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. This sequence change replaces alanine, which is neutral and non-polar, with valine, which is neutral and non-polar, at codon 248 of the DISP1 protein (p.Ala248Val). This variant is present in population databases (no rsID available, gnomAD 0.01%). This missense change has been observed in individual(s) with holoprosencephaly (PMID: 28640243). ClinVar contains an entry for this variant (Variation ID: 397657). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Possibly Damaging"; Align-GVGD: "Class C0"). |