Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Neuberg Centre For Genomic Medicine, |
RCV004771625 | SCV005382248 | uncertain significance | Spinocerebellar ataxia type 15/16 | 2023-05-20 | criteria provided, single submitter | clinical testing | The observed missense variant c.7852A>C(p.Thr2618Pro) in ITPRI gene has not been reported previously as a pathogenic variant nor as a benign variant, to our knowledge. The c.7852A>C variant is absent in gnomAD Exomes. The amino acid Threonine at position 2618 is changed to a Proline changing protein sequence and it might alter its composition and physico-chemical properties. Multiple lines of computational evidence (Polyphen, SIFT and Mutation Taster) predict a damaging effect on protein structure and function for this variant.The reference amino acid in ITPR1 is predicted as conserved by GERP++ and PhyloP across 100 vertebrates. For these reasons, this variant has been classified as Uncertain Significance. |