Total submissions: 10
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Eurofins Ntd Llc |
RCV000180334 | SCV000232746 | uncertain significance | not provided | 2015-06-03 | criteria provided, single submitter | clinical testing | |
Personalized Diabetes Medicine Program, |
RCV000445510 | SCV000536964 | likely benign | Monogenic diabetes | 2018-01-12 | criteria provided, single submitter | research | ACMG criteria: PP3 (2 predictors), BP4 (7 predictors), BP1 (missense in gene with truncating cause disease), Emory calls VUS, cases and controls similar frequency=likely benign |
Laboratory for Molecular Medicine, |
RCV000825702 | SCV000967148 | likely benign | not specified | 2017-08-23 | criteria provided, single submitter | clinical testing | p.Gly612Asp in exon 8 of ALMS1: This variant is not expected to have clinical si gnificance because it has been identified in 0.64% (63/9800) of African chromoso mes by the Exome Aggregation Consortium (ExAC, http://exac.broadinstitute.org; d bSNP rs148040591). |
Invitae | RCV001086118 | SCV001000876 | likely benign | Alstrom syndrome | 2024-01-31 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV000825702 | SCV001482073 | likely benign | not specified | 2022-08-08 | criteria provided, single submitter | clinical testing | Variant summary: ALMS1 c.1835G>A (p.Gly612Asp), also referred to as c.1841G>A (p.Gly614Asp) results in a non-conservative amino acid change in the encoded protein sequence. Three of four in-silico tools predict a benign effect of the variant on protein function. The variant allele was found at a frequency of 0.00042 in 249178 control chromosomes, predominantly at a frequency of 0.0065 within the African or African-American subpopulation in the gnomAD database, including 1 homozygotes. The observed variant frequency within African or African-American control individuals in the gnomAD database is approximately 3.6 fold of the estimated maximal expected allele frequency for a pathogenic variant in ALMS1 causing Alstrom Syndrome With Dilated Cardiomyopathy phenotype (0.0018), strongly suggesting that the variant is a benign polymorphism found primarily in populations of African or African-American origin. To our knowledge, no occurrence of c.1835G>A in individuals affected with Alstrom Syndrome With Dilated Cardiomyopathy and no experimental evidence demonstrating its impact on protein function have been reported. Sevenclinical diagnostic laboratories have submitted clinical-significance assessments for this variant to ClinVar after 2014 without evidence for independent evaluation (likely benign, n=6; VUS, n=1). Based on the evidence outlined above, the variant was classified as likely benign. |
Gene |
RCV000180334 | SCV001771979 | likely benign | not provided | 2021-09-02 | criteria provided, single submitter | clinical testing | |
Genetic Services Laboratory, |
RCV000825702 | SCV002070950 | likely benign | not specified | 2018-08-21 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV002408782 | SCV002716400 | benign | Cardiovascular phenotype | 2021-10-29 | criteria provided, single submitter | clinical testing | This alteration is classified as benign based on a combination of the following: seen in unaffected individuals, population frequency, intact protein function, lack of segregation with disease, co-occurrence, RNA analysis, in silico models, amino acid conservation, lack of disease association in case-control studies, and/or the mechanism of disease or impacted region is inconsistent with a known cause of pathogenicity. |
Clinical Genomics, |
RCV001086118 | SCV003928158 | uncertain significance | Alstrom syndrome | criteria provided, single submitter | research | Potent mutations in ALMS1 are associated with a rare condition called Alstrom syndrome. It can cause excessive eating, insulin resistance. However, no evidence is found to ascertain the role of rs148040591 in Alstrom syndrome yet. | |
Natera, |
RCV001086118 | SCV002080431 | benign | Alstrom syndrome | 2019-10-21 | no assertion criteria provided | clinical testing |