Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000493964 | SCV000582585 | pathogenic | not provided | 2018-07-02 | criteria provided, single submitter | clinical testing | The L457X variant in the CC2D2A gene has not been reported previously as a pathogenic variant nor as a benign variant, to our knowledge. This variant is predicted to cause loss of normal protein function either through protein truncation or nonsense-mediated mRNA decay. The L457X variant is not observed in large population cohorts (Lek et al., 2016). We interpret L457X as a pathogenic variant. |
Labcorp Genetics |
RCV003766778 | SCV004568515 | pathogenic | Familial aplasia of the vermis; Meckel-Gruber syndrome | 2023-01-17 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. ClinVar contains an entry for this variant (Variation ID: 429902). This variant has not been reported in the literature in individuals affected with CC2D2A-related conditions. This variant is not present in population databases (gnomAD no frequency). This sequence change creates a premature translational stop signal (p.Leu457*) in the CC2D2A gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in CC2D2A are known to be pathogenic (PMID: 19777577). |