Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001380418 | SCV001578483 | pathogenic | not provided | 2022-10-05 | criteria provided, single submitter | clinical testing | ClinVar contains an entry for this variant (Variation ID: 1068762). For these reasons, this variant has been classified as Pathogenic. Experimental studies have shown that this missense change affects CNGA1 function (PMID: 26802146). Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive. This missense change has been observed in individual(s) with autosomal recessive retinitis pigmentosa (PMID: 26802146; externalcommunication). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. It has also been observed to segregate with disease in related individuals. This variant is present in population databases (rs544588016, gnomAD 0.003%). This sequence change replaces glycine, which is neutral and non-polar, with arginine, which is basic and polar, at codon 513 of the CNGA1 protein (p.Gly513Arg). |
OMIM | RCV003222314 | SCV003841142 | pathogenic | Retinitis pigmentosa 49 | 2023-02-23 | no assertion criteria provided | literature only |