Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001451600 | SCV001655235 | likely benign | not provided | 2025-02-03 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV003388017 | SCV004100021 | uncertain significance | not specified | 2023-09-20 | criteria provided, single submitter | clinical testing | Variant summary: COL18A1 c.3920C>T (p.Ser1307Leu) results in a non-conservative amino acid change located in the collagenase non-helical region 10/endostatin domain (IPR010515) of the encoded protein sequence. Three of five in-silico tools predict a benign effect of the variant on protein function. The variant allele was found at a frequency of 0.0003 in 243722 control chromosomes, predominantly at a frequency of 0.0047 within the African or African-American subpopulation in the gnomAD database, suggesting the variant could be a benign polymorphism found primarily in individuals of African/African American ancestry. To our knowledge, no occurrence of c.3920C>T in individuals affected with Knobloch Syndrome 1 and no experimental evidence demonstrating its impact on protein function have been reported. One submitter has cited a clinical-significance assessment for this variant to ClinVar after 2014 and has classified the variant as likely benign. Based on the evidence outlined above, the variant was classified as VUS-possibly benign. |
Breakthrough Genomics, |
RCV001451600 | SCV005207601 | likely benign | not provided | criteria provided, single submitter | not provided | ||
Gene |
RCV001451600 | SCV005326740 | uncertain significance | not provided | 2024-02-08 | criteria provided, single submitter | clinical testing | Reported in an individual with Down syndrome and atrioventricular septal defect (PMID: 23040494); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 23040494) |