Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
ARUP Laboratories, |
RCV000506639 | SCV000605253 | uncertain significance | not specified | 2017-03-27 | criteria provided, single submitter | clinical testing | |
Center for Human Genetics, |
RCV000660289 | SCV000782317 | pathogenic | Hereditary pancreatitis | 2016-11-01 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000660289 | SCV000951976 | uncertain significance | Hereditary pancreatitis | 2021-02-04 | criteria provided, single submitter | clinical testing | This variant is present in population databases (rs576564400, ExAC 0.02%). This sequence change replaces threonine with isoleucine at codon 69 of the SPINK1 protein (p.Thr69Ile). The threonine residue is weakly conserved and there is a moderate physicochemical difference between threonine and isoleucine. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Experimental studies have shown that this missense change abolishes SPINK1 protein expression in an overexpression system (PMID: 22343981). This variant has been observed in an individual affected with alcoholic pancreatitis (PMID: 18182741) and in individuals with idiopathic chronic pancreatitis (PMID: 30420730). ClinVar contains an entry for this variant (Variation ID: 440299). |
Ambry Genetics | RCV000660289 | SCV002727685 | uncertain significance | Hereditary pancreatitis | 2021-03-10 | criteria provided, single submitter | clinical testing | The p.T69I variant (also known as c.206C>T), located in coding exon 4 of the SPINK1 gene, results from a C to T substitution at nucleotide position 206. The threonine at codon 69 is replaced by isoleucine, an amino acid with similar properties. This alteration was identified in multiple individuals with chronic pancreatitis (Rerknimitr R et al. JOP, 2008;9:33-6; Zou WB et al. Clin Transl Gastroenterol, 2018 11;9:204). This amino acid position is poorly conserved on limited sequence alignment. In addition, this alteration is predicted to be tolerated by in silico analysis. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |