Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001068304 | SCV001233408 | likely pathogenic | Stormorken syndrome; Combined immunodeficiency due to STIM1 deficiency; Myopathy with tubular aggregates | 2019-01-03 | criteria provided, single submitter | clinical testing | In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. This variant has been reported to affect STIM1 protein function (PMID: 25326555). This variant has been observed in individuals affected with tubular aggregate myopathy (TAM) and was observed to be de novo in one individual (PMID: 25326555). ClinVar contains an entry for this variant (Variation ID: 189363). This variant is not present in population databases (ExAC no frequency). This sequence change replaces asparagine with threonine at codon 80 of the STIM1 protein (p.Asn80Thr). The asparagine residue is moderately conserved and there is a small physicochemical difference between asparagine and threonine. |
OMIM | RCV000169764 | SCV000221328 | pathogenic | Myopathy, tubular aggregate, 1 | 2014-12-01 | no assertion criteria provided | literature only |