Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001891483 | SCV002159057 | likely pathogenic | Stormorken syndrome; Combined immunodeficiency due to STIM1 deficiency; Myopathy with tubular aggregates | 2022-08-16 | criteria provided, single submitter | clinical testing | In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C0"). ClinVar contains an entry for this variant (Variation ID: 1395833). This missense change has been observed in individual(s) with clinical features of autosomal dominant STIM1-related conditions (PMID: 28624464; Invitae). In at least one individual the variant was observed to be de novo. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces serine, which is neutral and polar, with glycine, which is neutral and non-polar, at codon 88 of the STIM1 protein (p.Ser88Gly). |
Clinical Genetics Laboratory, |
RCV004697156 | SCV005196853 | likely pathogenic | not provided | 2022-05-27 | criteria provided, single submitter | clinical testing | |
Laboratory of Molecular Genetics, |
RCV002287513 | SCV002569143 | pathogenic | Stormorken syndrome | 2022-09-05 | no assertion criteria provided | clinical testing |