Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
UNC Molecular Genetics Laboratory, |
RCV001374622 | SCV001571468 | uncertain significance | Alkuraya-Kucinskas syndrome | 2021-02-01 | criteria provided, single submitter | research | The KIAA1109 c.3046G>A (p.Gly1016Ser) is a missense variant that changes a single amino acid in the encoded protein from glycine to serine. This variant is present in unselected individuals in the general population with a global minor allele frequency of 0.0276% (77/279,004 alleles, 0 homozygotes). To our knowledge, this variant has not been previously reported in affected individuals in the literature. The resulting amino acid change has conflicting predictions of pathogenicity by in silico tools and the effect on protein function is unknown. Without additional clinical or functional evidence, this variant is considered a variant of uncertain significance. |
Al Jalila Children’s Genomics Center, |
RCV001374622 | SCV001984436 | uncertain significance | Alkuraya-Kucinskas syndrome | 2020-10-05 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV004037613 | SCV003945600 | uncertain significance | not specified | 2023-03-17 | criteria provided, single submitter | clinical testing | The c.3046G>A (p.G1016S) alteration is located in exon 24 (coding exon 24) of the KIAA1109 gene. This alteration results from a G to A substitution at nucleotide position 3046, causing the glycine (G) at amino acid position 1016 to be replaced by a serine (S). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |