Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Neuberg Centre For Genomic Medicine, |
RCV004723696 | SCV005329385 | uncertain significance | KINSSHIP syndrome | 2023-05-20 | criteria provided, single submitter | clinical testing | The observed missense variant c.127G>C (p.Asp43His) in AFF3 gene has not been reported previously as a pathogenic variant nor as a benign variant, to our knowledge. The p.Asp43His variant is absent in gnomAD Exomes. This variant has not been submitted to the ClinVar database. Multiple lines of computational evidence (Polyphen -Probably damaging, SIFT - Damaging and Mutation Taster - Polymorphism) predicts conflicting evidence on protein structure and function for this variant. The amino acid change p.Asp43His in AFF3 is predicted as conserved by GERP++ and PhyloP across 100 vertebrates. The amino acid Asp at position 43 is changed to a His changing protein sequence and it might alter its composition and physico-chemical properties. For these reasons, this variant has been classified as Variant of Uncertain Significance (VUS). |