Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Mendelics | RCV000990457 | SCV001141449 | uncertain significance | Rubinstein-Taybi syndrome due to CREBBP mutations | 2019-05-28 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV005056719 | SCV005697593 | uncertain significance | Rubinstein-Taybi syndrome due to EP300 haploinsufficiency | 2024-07-10 | criteria provided, single submitter | clinical testing | This variant, c.7014_7028del, results in the deletion of 5 amino acid(s) of the EP300 protein (p.His2338_Pro2342del), but otherwise preserves the integrity of the reading frame. This variant is not present in population databases (gnomAD no frequency). This variant has been observed in individual(s) with EP300-related conditions (PMID: 31337854). ClinVar contains an entry for this variant (Variation ID: 803704). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
3billion | RCV005056719 | SCV005904757 | uncertain significance | Rubinstein-Taybi syndrome due to EP300 haploinsufficiency | 2023-11-15 | criteria provided, single submitter | clinical testing | The variant is not observed in the gnomAD v2.1.1 dataset. Predicted Consequence/Location: Inframe deletion located in a nonrepeat region: predicted to change the length of the protein and disrupt normal protein function. The variant has been reported to be associated with EP300 related disorder (PMID: 31337854). However, the evidence of pathogenicity is insufficient at this time. Therefore, this variant is classified as VUS according to the recommendation of ACMG/AMP guideline. |
Prevention |
RCV004740528 | SCV005363691 | uncertain significance | EP300-related disorder | 2024-09-05 | no assertion criteria provided | clinical testing | The EP300 c.7014_7028del15 variant is predicted to result in an in-frame deletion (p.His2338_Pro2342del). This variant was reported in an individual with Cornelia de Lange syndrome (Aoi et al 2019. PubMed ID: 31337854). This variant has not been reported in a large population database, indicating this variant is rare. At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |