Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Neuberg Centre For Genomic Medicine, |
RCV004785857 | SCV005400936 | uncertain significance | Spinocerebellar ataxia 45 | 2023-06-22 | criteria provided, single submitter | clinical testing | The observed missense variant c.7652G>A(p.Arg2551Lys) in FAT2 gene has not been reported previously as a pathogenic variant nor as a benign variant, to our knowledge. The (p.Arg2551Lys) variant is reported with 0.0004% allele frequencyin gnomAD Exomes. The amino acid Arg at position 2551 is changed to a Lys changing protein sequence and it might alter its composition and physico-chemical properties. The reference amino acid p.Arg2551Lys in FAT2 is predicted as conserved by GERP++ and PhyloP across 100 vertebrates.Computational evidence (Polyphen-Benign, SIFT-Tolerated and Mutation Taster-disease causing) predicts conflicting evidence on protein structure and function for this variant. For these reasons, this variant has been classified as Uncertain Significance. |