Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000521309 | SCV000621212 | likely pathogenic | not provided | 2017-09-27 | criteria provided, single submitter | clinical testing | The A204G variant in the ACTG1 gene has not been reported previously as a pathogenic variant, nor as a benign variant, to our knowledge. The A204G variant is not observed in the gnomAD dataset (Lek et al., 2016). The A204G variant is a conservative amino acid substitution, which occurs at a position that is conserved across species. In silico analysis predicts this variant is probably damaging to the protein structure/function. We interpret A204G as a likely pathogenic variant. |
Undiagnosed Diseases Network, |
RCV001255976 | SCV001432753 | likely pathogenic | Baraitser-winter syndrome 2 | 2020-07-14 | criteria provided, single submitter | clinical testing | This is a de novo heterozygous missense variant in ACTG1. This variant is absent from internal and external control samples. It is a probably damaging missense variant with a PolyPhen2 score of 0.916. ACTG1 is an intolerant gene with an RVIS score of 2.8. This site is strongly conserved with a GERP++ RS score of 4.56. Note: the patient supporting this variant interpretation is the same patient reported by GeneDx in SCV000621212.2. |