Total submissions: 8
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Human Genetics, |
RCV001095368 | SCV000999252 | pathogenic | neuro-ectodermal phenotype | 2019-11-28 | criteria provided, single submitter | research | |
Equipe Genetique des Anomalies du Developpement, |
RCV001526531 | SCV001736953 | pathogenic | Ectodermal dysplasia with facial dysmorphism and acral, ocular, and brain anomalies | criteria provided, single submitter | clinical testing | ||
Equipe Genetique des Anomalies du Developpement, |
RCV001526536 | SCV001736958 | pathogenic | Hemihypertrophy | criteria provided, single submitter | clinical testing | ||
Gene |
RCV001539108 | SCV001756849 | pathogenic | not provided | 2022-11-25 | criteria provided, single submitter | clinical testing | Identified in multiple unrelated patients as a somatic mosaic variant in skin tissue with hypopigmented areas of the skin, dental anomalies, body asymmetry, hemihypotrophy and brain magnetic resonance imaging (MRI) anomalies in published literature (Vabres et al., 2019; Yigit et al., 2019); Published functional studies demonstrate a inactivating effect of the Glu47Lys RHOA variant (Vabres et al., 2019); Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 31570889, 31821646, 32335911) |
Baylor Genetics | RCV001526531 | SCV003836018 | pathogenic | Ectodermal dysplasia with facial dysmorphism and acral, ocular, and brain anomalies | 2022-11-06 | criteria provided, single submitter | clinical testing | |
Invitae | RCV001539108 | SCV004629390 | pathogenic | not provided | 2023-10-05 | criteria provided, single submitter | clinical testing | This sequence change replaces glutamic acid, which is acidic and polar, with lysine, which is basic and polar, at codon 47 of the RHOA protein (p.Glu47Lys). This variant is not present in population databases (gnomAD no frequency). This missense change has been observed in individual(s) with RHOA-related conditions (PMID: 31570889, 31821646). In at least one individual the variant was observed to be de novo. ClinVar contains an entry for this variant (Variation ID: 695069). An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. Experimental studies have shown that this missense change affects RHOA function (PMID: 31570889). For these reasons, this variant has been classified as Pathogenic. |
OMIM | RCV001526531 | SCV001134930 | pathogenic | Ectodermal dysplasia with facial dysmorphism and acral, ocular, and brain anomalies | 2020-01-29 | no assertion criteria provided | literature only | |
Undiagnosed Diseases Network, |
RCV001526531 | SCV004812028 | pathogenic | Ectodermal dysplasia with facial dysmorphism and acral, ocular, and brain anomalies | 2023-02-14 | no assertion criteria provided | clinical testing |