Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Revvity Omics, |
RCV003144279 | SCV003834453 | uncertain significance | not provided | 2021-04-07 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV003144279 | SCV004293136 | uncertain significance | not provided | 2024-06-22 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with cysteine, which is neutral and slightly polar, at codon 338 of the ATP6V1A protein (p.Arg338Cys). This variant is present in population databases (no rsID available, gnomAD 0.0009%). This missense change has been observed in individual(s) with autosomal recessive cutis laxa (PMID: 28065471). ClinVar contains an entry for this variant (Variation ID: 417772). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt ATP6V1A protein function with a positive predictive value of 80%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
OMIM | RCV000477739 | SCV000564223 | pathogenic | Autosomal recessive cutis laxa type 2D | 2017-03-27 | no assertion criteria provided | literature only |