Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV003558784 | SCV004293927 | pathogenic | not provided | 2023-08-09 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Gln27*) in the ATP6V1B1 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in ATP6V1B1 are known to be pathogenic (PMID: 9916796, 18368028). This variant is not present in population databases (gnomAD no frequency). This premature translational stop signal has been observed in individual(s) with clinical features of ATP6V1B1-related disorders (PMID: 28844315). ClinVar contains an entry for this variant (Variation ID: 988216). For these reasons, this variant has been classified as Pathogenic. |
Sydney Genome Diagnostics, |
RCV001328240 | SCV001449187 | likely pathogenic | Renal tubular acidosis | 2014-04-18 | no assertion criteria provided | clinical testing |