Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV004692588 | SCV005196438 | uncertain significance | Hereditary thrombocytopenia and hematologic cancer predisposition syndrome | 2024-08-12 | reviewed by expert panel | curation | NM_001754.5(RUNX1):c.872T>C (p.Ile291Thr) is a missense variant which is reported at a MAF of 0.00007236 (0.007%, 3/41460 alleles) in the African/African American sub-population of the gnomAD v3.1.2 cohort and does not meet the threshold for BA1 (≥0.0015) or BS1 (0.00015 - 0.0015). The variant has a REVEL score of 0.228, which meets the threshold for BP4 (<0.50). In summary, the clinical significance of this variant is uncertain. ACMG/AMP criteria applied, as specified by the Myeloid Malignancy Variant Curation Expert Panel for RUNX1: BP4. |
Labcorp Genetics |
RCV001339101 | SCV001532822 | uncertain significance | Hereditary thrombocytopenia and hematological cancer predisposition syndrome associated with RUNX1 | 2024-09-16 | criteria provided, single submitter | clinical testing | This sequence change replaces isoleucine, which is neutral and non-polar, with threonine, which is neutral and polar, at codon 291 of the RUNX1 protein (p.Ile291Thr). This variant is present in population databases (rs371026644, gnomAD 0.008%). This variant has not been reported in the literature in individuals affected with RUNX1-related conditions. ClinVar contains an entry for this variant (Variation ID: 1036141). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is not expected to disrupt RUNX1 protein function with a negative predictive value of 80%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Baylor Genetics | RCV004570812 | SCV005055494 | uncertain significance | Acute myeloid leukemia | 2023-12-14 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV004960811 | SCV005495307 | uncertain significance | Inborn genetic diseases | 2024-11-24 | criteria provided, single submitter | clinical testing | The p.I291T variant (also known as c.872T>C), located in coding exon 7 of the RUNX1 gene, results from a T to C substitution at nucleotide position 872. The isoleucine at codon 291 is replaced by threonine, an amino acid with similar properties. This amino acid position is conserved. In addition, the in silico prediction for this alteration is inconclusive. Based on the available evidence, the clinical significance of this variant remains unclear. |