Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Laboratory of Medical Genetics, |
RCV000789039 | SCV000928380 | likely pathogenic | Stickler syndrome, type I, nonsyndromic ocular | 2018-10-10 | criteria provided, single submitter | clinical testing | PM1, PM2, PP2, PP3 |
3billion | RCV000789039 | SCV005903733 | uncertain significance | Stickler syndrome, type I, nonsyndromic ocular | 2023-07-10 | criteria provided, single submitter | clinical testing | The variant is not observed in the gnomAD v2.1.1 dataset. Predicted Consequence/Location: Missense changes are a common disease-causing mechanism. In silico tool predictions suggest damaging effect of the variant on gene or gene product (REVEL: 0.74; 3Cnet: 0.13). Same nucleotide change resulting in same amino acid change has been previously reported to be associated with COL2A1 related disorder (ClinVar ID: VCV000637048 /PMID: 34008892). However, the evidence of pathogenicity is insufficient at this time. Therefore, this variant is classified as VUS according to the recommendation of ACMG/AMP guideline. |