Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV001587154 | SCV001820835 | likely pathogenic | not provided | 2024-11-05 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; Has not been previously published as pathogenic or benign to our knowledge; This variant is associated with the following publications: (PMID: 25240749) |
Labcorp Genetics |
RCV001587154 | SCV002277126 | pathogenic | not provided | 2025-01-15 | criteria provided, single submitter | clinical testing | This sequence change replaces glycine, which is neutral and non-polar, with glutamic acid, which is acidic and polar, at codon 838 of the COL11A1 protein (p.Gly838Glu). This variant is present in population databases (rs372419698, gnomAD 0.007%). This missense change has been observed in individual(s) with autosomal dominant Stickler syndrome (internal data). It has also been observed to segregate with disease in related individuals. ClinVar contains an entry for this variant (Variation ID: 1216773). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is expected to disrupt COL11A1 protein function with a positive predictive value of 80%. For these reasons, this variant has been classified as Pathogenic. |
Genome |
RCV001825009 | SCV002075112 | not provided | Marshall syndrome; Stickler syndrome type 2; Fibrochondrogenesis 1; Hearing loss, autosomal dominant 37 | no assertion provided | phenotyping only | Variant interpreted as Likely pathogenic and reported on 06-17-2020 by Lab or GTR ID 26957. GenomeConnect assertions are reported exactly as they appear on the patient-provided report from the testing laboratory. GenomeConnect staff make no attempt to reinterpret the clinical significance of the variant. | |
Autoinflammatory diseases unit, |
RCV004770182 | SCV005381979 | likely pathogenic | Stickler syndrome type 2 | 2024-09-25 | no assertion criteria provided | clinical testing |