Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Illumina Laboratory Services, |
RCV003315111 | SCV004014676 | likely pathogenic | Stickler syndrome type 2 | 2023-04-12 | criteria provided, single submitter | clinical testing | The COL11A1 c.3874_3892delinsT (p.Pro1292_Pro1298delinsSer) variant results in an in-frame deletion of six amino acids and the substitution of proline at amino acid position 1292 with serine. To our knowledge, this variant has not been reported in the peer-reviewed literature. This variant is not found in version 2.1.1 or version 3.1.2 of the Genome Aggregation Database. The p.Pro1292_Pro1298delinsSer variant lies within the triple helix domain of the protein, which interacts with similar domains in collagens encoded by COL2A1 and COL11A2 to form heterotrimeric type XI collagen (PMID: 35741851). Based on the available evidence, the c.3874_3892delinsT (p.Pro1292_Pro1298delinsSer) variant is classified as likely pathogenic for Stickler syndrome. |