Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Human Genetics, |
RCV003322734 | SCV004027831 | likely pathogenic | Arrhythmogenic right ventricular dysplasia 10 | 2023-06-28 | criteria provided, single submitter | clinical testing | Criteria applied: PVS1,PM2_SUP |
Invitae | RCV003322734 | SCV004505173 | pathogenic | Arrhythmogenic right ventricular dysplasia 10 | 2023-02-26 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Asn462Metfs*6) in the DSG2 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in DSG2 are known to be pathogenic (PMID: 17105751, 31386562). For these reasons, this variant has been classified as Pathogenic. This variant has not been reported in the literature in individuals affected with DSG2-related conditions. This variant is not present in population databases (gnomAD no frequency). |