Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
3billion | RCV000192162 | SCV002059029 | pathogenic | Alexander disease | 2022-01-03 | criteria provided, single submitter | clinical testing | Same nucleotide change resulting in same amino acid change has been previously reported to be associated with GFAP related disorder (ClinVar ID: VCV000066431, PMID:21533827 PS1_S). The variant is located in a well-established functional domain or exonic hotspot, where pathogenic variants have frequently reported (PM1_M). It is not observed in the gnomAD v2.1.1 dataset (PM2_M). In silico tool predictions suggest damaging effect of the variant on gene or gene product (REVEL: 0.955, 3CNET: 0.992, PP3_P). A missense variant is a common mechanism associated with Alexander disease (PP2_P). Therefore, this variant is classified as pathogenic according to the recommendation of ACMG/AMP guideline. |
Epithelial Biology; Institute of Medical Biology, |
RCV000056824 | SCV000087937 | not provided | not provided | no assertion provided | not provided | ||
Gene |
RCV000192162 | SCV000223027 | pathogenic | Alexander disease | 2015-01-08 | no assertion criteria provided | literature only |