Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV003728017 | SCV004534902 | uncertain significance | not provided | 2022-11-12 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Experimental studies have shown that this missense change affects GLRA2 function (PMID: 35294868). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt GLRA2 protein function. ClinVar contains an entry for this variant (Variation ID: 1334405). This missense change has been observed in individual(s) with GLRA2-related conditions (PMID: 35294868). This variant is present in population databases (rs748764171, gnomAD 0.001%). This sequence change replaces arginine, which is basic and polar, with cysteine, which is neutral and slightly polar, at codon 252 of the GLRA2 protein (p.Arg252Cys). |
Center for Genomic Medicine, |
RCV002246530 | SCV004806941 | uncertain significance | Intellectual developmental disorder, X-linked, syndromic, Pilorge type | 2024-03-26 | criteria provided, single submitter | clinical testing | |
Wangler Lab, |
RCV001813916 | SCV002056022 | uncertain significance | See cases | 2022-01-10 | no assertion criteria provided | research | Marcogliese et al., (2022) have identified 13 unrelated subjects with a variable neurodevelopmental disorder with or without autistic features. The c.754C>T results in an amino acid change of p.Arg252Cys. This variant was shown to act as Loss of Function in functional studies using Drosophila. This variant was identified in a male proband with maternal inheritance (unaffected mother). |
OMIM | RCV002246530 | SCV002520428 | pathogenic | Intellectual developmental disorder, X-linked, syndromic, Pilorge type | 2022-04-26 | no assertion criteria provided | literature only |