Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Human Genetics, |
RCV003128370 | SCV003804648 | likely pathogenic | Epicanthus; Inversion of nipple; Cerebellar ataxia; Atypical behavior; Focal-onset seizure; Hypermetropia; Pes planus; Short philtrum; Macrocephaly; Generalized-onset seizure; Moderate global developmental delay | 2023-01-31 | criteria provided, single submitter | clinical testing | This variant was identified as de novo (maternity and paternity confirmed)._x000D_ Criteria applied: PS2_MOD, PM5, PM2_SUP, PP2, PP3 At the affected amino acid position, another amino acid substitution is already described as pathogenic in the databases for disease-causing variants and in the literature (PM5,c.1366G>C; (p.Val456Leu), Salpietro et al., 2022, PMID: 36318112) |