Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002004821 | SCV002231995 | pathogenic | not provided | 2023-11-20 | criteria provided, single submitter | clinical testing | This sequence change replaces threonine, which is neutral and polar, with methionine, which is neutral and non-polar, at codon 1041 of the LRP5 protein (p.Thr1041Met). This variant is present in population databases (no rsID available, gnomAD 0.002%). This missense change has been observed in individuals with clinical features of autosomal dominant exudative retinopathy (PMID: 30452590; Invitae). ClinVar contains an entry for this variant (Variation ID: 1450334). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt LRP5 protein function with a positive predictive value of 95%. For these reasons, this variant has been classified as Pathogenic. |
Genome Diagnostics Laboratory, |
RCV002276951 | SCV002564889 | uncertain significance | Osteogenesis imperfecta | 2018-10-01 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV005050476 | SCV005684848 | likely pathogenic | Bone mineral density quantitative trait locus 1; Exudative vitreoretinopathy 4; Worth disease; Autosomal dominant osteopetrosis 1; Osteoporosis with pseudoglioma; Polycystic liver disease 4 with or without kidney cysts | 2024-04-29 | criteria provided, single submitter | clinical testing |